Table 1

The six clinical forms of hypophosphatasia.

Clinical form
Inheritance
Bone symptoms
Dental symptoms
Clinical diagnosis

Perinatal lethal
AR
Hypomineralization
Osteochondral spurs
na
Radiographs
Ultrasonography
Prenatal benign
AD
Bowing of long bones
Benign post-natal
na
Ultrasonography
Clinical examination
Infantile
AR
Craniosynostosis
Hypomineralization
Rachitic ribs
Hypercalciuria
Premature loss of
deciduous teeth
Clinical examination
Biology (serum AP activity, PEA and PLP).
Radiographs
Childhood
AR (frequent) or AD (rare)
Short stature Skeletal
deformity Waddling gait
Bone pain/fractures
Premature loss of
deciduous teeth

Adult
AR or AD
Stress fractures: metatarsal,
tibia Osteoarthritis
+/-

Odontohypophosphatasia
AR or AD
Loss of alveolar bone
Exfoliation (incisors).
Reduced thickness of the dentin.
Enlarged pulp chambers of teeth.
Dental caries
Clinical examination.
Biology (serum AP activity, PEA and PLP).

na: not applicable;

AR : autosomal recessive;

AD: autosomal dominant.

Mornet Orphanet Journal of Rare Diseases 2007 2:40   doi:10.1186/1750-1172-2-40